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Dopamine Modulates Adaptive Forgetting in Medial Prefrontal Cortex

Francisco Tomás Gallo, Maria Belen Zanoni, Azul Silva, Juan Facundo Morici, Magdalena Miranda, Michael C. Anderson, Noelia Weisstaub, Pedro Bekinschtein

2022Journal of Neuroscience19 citationsDOIOpen Access PDF

Abstract

<h3>INTRODUCTION</h3> An intronic germline mutation in the <i>MSH2</i> gene, A→T at nt942+3, interferes with the exon 5 donor splicing mechanism leading to a mRNA lacking exon 5. This mutation causes typical hereditary non-polyposis colorectal cancer (HNPCC) and has been observed in numerous probands and families world wide. Recurrent mutations either arise repeatedly de novo or emanate from ancestral founding mutational events. The A→T mutation had previously been shown to be enriched in the population of Newfoundland where most families shared a founder mutation. In contrast, in England, haplotypes failed to suggest a founder effect. If the absence of a founder effect could be proven world wide, the frequent de novo occurrence of the mutation would constitute an unexplored predisposition. <h3>METHODS</h3> We studied 10 families from England, Italy, Hong Kong, and Japan with a battery of intragenic and flanking polymorphic single nucleotide and microsatellite markers. <h3>RESULTS</h3> Haplotype sharing was not apparent, even within the European and Asian kindreds. Our marker panel was sufficient to detect a major mutation arising within the past several thousand generations. <h3>DISCUSSION</h3> As a more ancient founder is implausible, we conclude that the A→T mutation at nt942+3 of <i>MSH2</i> occurs de novo with a relatively high frequency. We hypothesise that it arises as a consequence of misalignment at replication or recombination caused by a repeat of 26 adenines, of which the mutated A is the first. It is by far the most common recurrent de novo germline mutation yet to be detected in a human mismatch repair gene, accounting for 11% of all known pathogenic<i>MSH2</i> mutations.

Topics & Concepts

GeneticsFounder effectBiologyHaplotypeMutationMSH2PopulationExonGermline mutationDNA mismatch repairGeneDNA repairGenotypeMedicineEnvironmental healthMemory Processes and InfluencesGenetic Associations and EpidemiologyGenomics and Rare Diseases
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