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The genetics and disease mechanisms of rhegmatogenous retinal detachment

Birgit Marlies Govers, Ramon A. C. van Huet, Susanne Roosing, Sander Keijser, Leonoor I. Los, Anneke I. den Hollander, B. Jeroen Klevering

2023Progress in Retinal and Eye Research39 citationsDOIOpen Access PDF

Abstract

Rhegmatogenous retinal detachment (RRD) is a sight threatening condition that warrants immediate surgical intervention. To date, 29 genes have been associated with monogenic disorders involving RRD. In addition, RRD can occur as a multifactorial disease through a combined effect of multiple genetic variants and non-genetic risk factors. In this review, we provide a comprehensive overview of the spectrum of hereditary disorders involving RRD. We discuss genotype-phenotype correlations of these monogenic disorders, and describe genetic variants associated with RRD through multifactorial inheritance. Furthermore, we evaluate our current understanding of the molecular disease mechanisms of RRD-associated genetic variants on collagen proteins, proteoglycan versican, and the TGF-β pathway. Finally, we review the role of genetics in patient management and prevention of RRD. We provide recommendations for genetic testing and prophylaxis of at-risk patients, and hypothesize on novel therapeutic approaches beyond surgical intervention.

Topics & Concepts

Retinal detachmentDiseaseMedicineBioinformaticsGenetic variantsPhenotypeGeneticsGenotypeBiologyGenePathologyOphthalmologyRetinalRetinal and Macular SurgeryConnective tissue disorders researchChild Abuse and Related Trauma
The genetics and disease mechanisms of rhegmatogenous retinal detachment | Litcius