Litcius/Paper detail

Genome-wide Enrichment of <i>TERT</i> Rare Variants in Idiopathic Pulmonary Fibrosis Patients of Latino Ancestry

David Zhang, Qi Li, Gundula Povysil, Chad A. Newton, Toby M. Maher, Philip L. Molyneaux, Imre Noth, Fernando J. Martínez, Ganesh Raghu, Jamie L. Todd, Scott M. Palmer, Adam Platt, Slavé Petrovski, David B. Goldstein, Christine Kim Garcia

2022American Journal of Respiratory and Critical Care Medicine12 citationsDOIOpen Access PDF

Abstract

Genome-wide rare variant studies of IPF patients of non-European ancestry have been understudied. Here, we evaluate the enrichment of rare genetic variants of 241 unrelated non-European cases, representing individuals of Latino, African, South Asian, East Asian, and Other Admixed ancestry. Gene burden analysis of deleterious rare (protein-truncating and missense) variants demonstrate an excess of TERT rare damaging variants (OR 67.1, 95% CI [23.1, 195.0], P = 9.4 x 10-14) in non-European subjects. Analysis by ancestry demonstrated an excess of rare, damaging TERT variants in the Latino subgroup (OR 80.9, 95% CI [17.3, 383.8], P = 2.6 x 10-8). Although the non-European group did not show enrichment of PARN, RTEL1, and KIF15 rare deleterious variants, these groups all showed a trend in the same direction as the European ancestry group. For TERT and KIF15, the inclusion of IPF patients of non-European ancestry led to a higher odds ratios and increased evidence in favor of rare deleterious variant contributions, thus demonstrating the increased power of multi-ethnic studies over single-ethnicity studies. To our knowledge, this is the first study that confirms the involvement of rare deleterious TERT variants for IPF patients of Latino and non-European ancestry. To better understand the genetic underpinnings of IPF patients of all ancestries, additional work will be needed to broaden patient recruitment to normalize imbalances.

Topics & Concepts

MedicineIdiopathic pulmonary fibrosisGenomeGenome-wide association studyInternal medicineGeneticsGenotypeLungSingle-nucleotide polymorphismGeneBiologyInterstitial Lung Diseases and Idiopathic Pulmonary Fibrosis