Litcius/Paper detail

GnRH Deficient Patients With Congenital Hypogonadotropic Hypogonadism: Novel Genetic Findings in ANOS1, RNF216, WDR11, FGFR1, CHD7, and POLR3A Genes in a Case Series and Review of the Literature

Vassos Neocleous, Pavlos Fanis, Meropi Toumba, George A. Tanteles, Melpo Schiza, Feride Cinarli, Nicolas C. Nicolaides, Anastasis Oulas, George M. Spyrou, Christos S. Mantzoros, Dimitriοs Vlachakis, Nicos Skordis, Leonidas A. Phylactou

2020Frontiers in Endocrinology33 citationsDOIOpen Access PDF

Abstract

This report embraces the description of novel and previously reported rare pathogenic variants in a series of genes known to be implicated in the biological development of CHH. Notably, patients with CHH can harbor pathogenic rare variants in more than one gene which raises the hypothesis of locus-locus interactions providing evidence for digenic inheritance. The identification of such aberrations by NGS can be very informative for the management and future planning of these patients.

Topics & Concepts

Hypogonadotropic hypogonadismKallmann syndromeGeneticsExome sequencingGeneLocus (genetics)BiologyIn silicoGNRHRDisease gene identificationExomeCandidate geneBioinformaticsMutationMedicineDiseaseGonadotropin-releasing hormoneInternal medicineEndocrinologyHormoneLuteinizing hormoneInfectious disease (medical specialty)Coronavirus disease 2019 (COVID-19)Congenital Ear and Nasal AnomaliesHypothalamic control of reproductive hormonesGenomic variations and chromosomal abnormalities