Litcius/Paper detail

First heterozygous<i>NOP10</i>mutation in familial pulmonary fibrosis

Caroline Kannengiesser, Effrosyni D. Manali, Patrick Revy, Isabelle Callebaut, Ibrahima Ba, Adrien Borgel, Claire Oudin, Aggeliki Haritou, Lykourgos Kolilekas, Katerina Malagari, Raphaël Borie, Élodie Lainey, Cathérine Boileau, Bruno Crestani, Spyros A. Papiris

2020European Respiratory Journal29 citationsDOIOpen Access PDF

Abstract

<b>We provide first evidence that a heterozygous <i>NOP10</i> mutation (c.17A&gt;G,p.Tyr6Cys) identified in a large family co-segregates with adult-onset familial PF and predisposes to short telomere syndrome (familial PF, liver, haematological diseases)</b>http://bit.ly/2wvXsUd

Topics & Concepts

MedicineMutationTelomereHeterozygote advantageGeneticsGenotypeDNAGeneBiologyInterstitial Lung Diseases and Idiopathic Pulmonary FibrosisMedical Imaging and Pathology StudiesRNA modifications and cancer