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A vicious cycle of bisretinoid formation and oxidation relevant to recessive Stargardt disease

Jin Zhao, Hye Jin Kim, Keiko Ueda, Kevin Zhang, Diego Montenegro, Joshua L. Dunaief, Janet R. Sparrow

2021Journal of Biological Chemistry27 citationsDOIOpen Access PDF

Abstract

mice. In neural retina of the mutant mice, reduced Tfrc mRNA was also an indicator of retinal iron overload. Thus iron chelation may defend retina when bisretinoid toxicity is implicated in disease processes.

Topics & Concepts

ChemistryRetinalReactive oxygen speciesDeferiproneRetinaFerritinBiochemistryBiophysicsPhotochemistryDeferoxamineBiologyNeuroscienceRetinal Diseases and TreatmentsRetinal Development and DisordersRetinoids in leukemia and cellular processes
A vicious cycle of bisretinoid formation and oxidation relevant to recessive Stargardt disease | Litcius