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Safety and Disease Monitoring Biomarkers in Duchenne Muscular Dystrophy: Results From A Phase Ii Trial

Kathryn R. Wagner, M. Guglieri, Shashi K. Ramaiah, Lawrence Charnas, Shannon Marraffino, Michael Binks, Vishal S. Vaidya, Jeffrey Palmer, Richard A. Goldstein, Francesco Muntoni

2021Biomarkers in Medicine18 citationsDOIOpen Access PDF

Abstract

Aim: Evaluate the utility of glutamate dehydrogenase (GLDH) and cardiac troponin I as safety biomarkers, and creatine kinase and muscle injury panel as muscle health biomarkers in Duchenne muscular dystrophy. Patients & methods: Data were collected during a Phase II trial of domagrozumab. Results: GLDH was a more specific biomarker for liver injury than alanine aminotransferase. Cardiac troponin I elevations were variable and not sustained, limiting its applicability as a biomarker. Muscle injury panel biomarkers were no more informative than creatine kinase as a muscle health biomarker. Conclusion: Results support the use of GLDH as a specific biomarker for liver injury in patients with Duchenne muscular dystrophy. Clinical trial registration: ClinicalTrials.gov, NCT02310763.

Topics & Concepts

Duchenne muscular dystrophyMedicineBiomarkerCreatine kinaseMuscular dystrophyTroponinInternal medicineTroponin IPathologyMyocardial infarctionBiochemistryBiologyMuscle Physiology and DisordersNutrition and Health in AgingMuscle metabolism and nutrition
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