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Population sequencing data reveal a compendium of mutational processes in the human germ line

Vladimir B. Seplyarskiy, Ruslan Soldatov, Evan Koch, Ryan J. McGinty, Jakob M. Goldmann, Ryan D. Hernandez, Kathleen C. Barnes, Adolfo Correa, Esteban G. Burchard, Patrick T. Ellinor, Stephen T. McGarvey, Braxton D. Mitchell, Ramachandran S. Vasan, Susan Redline, Edwin K. Silverman, Scott T. Weiss, Donna K. Arnett, John Blangero, Eric Boerwinkle, Jiang He, Courtney G. Montgomery, D. C. Rao, Jerome I. Rotter, Kent D. Taylor, Jennifer A. Brody, Yii‐Der Ida Chen, Lisa de las Fuentes, Chii‐Min Hwu, Stephen S. Rich, Ani Manichaikul, Josyf C. Mychaleckyj, Nicholette D. Palmer, Jennifer A. Smith, Sharon L. R. Kardia, Patricia A. Peyser, Lawrence F. Bielak, Timothy D. O’Connor, Leslie S. Emery, TOPMed Population Genetics Working Group, Christian Gilissen, Wendy S.W. Wong, Peter V. Kharchenko, Shamil Sunyaev

2021Science74 citationsDOIOpen Access PDF

Abstract

Biological mechanisms underlying human germline mutations remain largely unknown. We statistically decompose variation in the rate and spectra of mutations along the genome using volume-regularized nonnegative matrix factorization. The analysis of a sequencing dataset (TOPMed) reveals nine processes that explain the variation in mutation properties between loci. We provide a biological interpretation for seven of these processes. We associate one process with bulky DNA lesions that are resolved asymmetrically with respect to transcription and replication. Two processes track direction of replication fork and replication timing, respectively. We identify a mutagenic effect of active demethylation primarily acting in regulatory regions and a mutagenic effect of long interspersed nuclear elements. We localize a mutagenic process specific to oocytes from population sequencing data. This process appears transcriptionally asymmetric.

Topics & Concepts

GeneticsBiologyGermlineMutationHuman genomeComputational biologyGenomeGenomicsCompendiumHuman genetic variationPopulation1000 Genomes ProjectGeneSingle-nucleotide polymorphismGenotypeMedicineEnvironmental healthHistoryArchaeologyCancer Genomics and DiagnosticsEpigenetics and DNA MethylationGenomics and Rare Diseases