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<i>SLC12A2</i> mutations cause NKCC1 deficiency with encephalopathy and impaired secretory epithelia

Tommy Stödberg, Måns Magnusson, Nicole Lesko, Anna Wredenberg, Daniel Martín Muñoz, Henrik Stranneheim, Anna Wedell

2020Neurology Genetics33 citationsDOIOpen Access PDF

Abstract

OBJECTIVE: To describe the phenotype in 2 sisters with a rare constellation of neurologic symptoms and secretory impairments and to identify the etiology by the use of whole-genome sequencing (WGS). METHODS: After an extensive workup failed to reveal the cause of disease, in a girl with a previously not reported phenotype, WGS of the proband, her diseased older sister, an older healthy brother, and their parents was performed, and potentially pathogenic variants were analyzed. RESULTS: were identified that follow an autosomal recessive inheritance pattern. CONCLUSIONS: as causing human disease and adds data regarding the neurologic phenotype.

Topics & Concepts

ProbandHypotoniaPhenotypeMedicineGlobal developmental delayCompound heterozygosityEncephalopathyPathologyGeneticsBiologyInternal medicineMutationGeneRNA regulation and diseaseGenetics and Neurodevelopmental DisordersGenomics and Rare Diseases