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Spatial and Temporal Distribution of White Matter Lesions in NOTCH2NLC-Related Neuronal Intranuclear Inclusion Disease

Shaoping Zhong, Beini Fei, Jingzhen Liang, Yangye Lian, Jing Wang, Ying Liu, Yuwen Zhang, Jianying Liu, Xin Wang, Jing Ding

2025Neurology14 citationsDOI

Abstract

BACKGROUND AND OBJECTIVES: -related NIID. METHODS: test, Mann-Whitney test, or correlation analysis. WML development patterns were summarized based on the longitudinal observation of MRI characteristics. RESULTS: = 0.048). Longitudinal MRI retrospection in 7 patients over an average of 9.6 ± 2.9 years revealed 3 gradually progressed WML patterns: periventricular-subcortical, periventricular-dominant, and corticomedullary junction-dominant. In addition, 3 patients experienced rapid WML expansion associated with mitochondrial encephalomyopathy with lactic acidosis and stroke (MELAS)-like episodes. DISCUSSION: Our analysis revealed the radiologic characteristics and spatial distribution of WMLs and demonstrated significant correlations between FLAIR hyperintensity volume and age/cognitive levels in NIID. Long-term retrospection revealed 3 types of gradual WML expansion patterns while MELAS-like episodes cause rapid WML aggravation. Although results should be confirmed in a larger cohort, these insights enhance understanding of NIID's clinical-radiologic relationships and pathogenesis.

Topics & Concepts

White matterDistribution (mathematics)Spatial distributionNeuroscienceDiseasePathologyMedicineBiologyMagnetic resonance imagingGeographyRadiologyMathematicsRemote sensingMathematical analysisCerebrovascular and genetic disordersGenetic Neurodegenerative DiseasesRNA regulation and disease