Litcius/Paper detail

Measurement of 17-Hydroxyprogesterone by LCMSMS Improves Newborn Screening for CAH Due to 21-Hydroxylase Deficiency in New Zealand

Mark de Hora, Natasha Heather, Tejal Patel, Lauren G. Bresnahan, Dianne Webster, Paul L. Hofman

2020International Journal of Neonatal Screening26 citationsDOIOpen Access PDF

Abstract

The positive predictive value of newborn screening for congenital adrenal hyperplasia due to 21-hydroxylase deficiency was <2% in New Zealand. This is despite a bloodspot second-tier immunoassay method for 17-hydroxyprogesterone measurement with an additional solvent extract step to reduce the number of false positive screening tests. We developed a liquid chromatography tandem mass spectrometry (LCMSMS) method to measure 17-hydroxyprogesterone in bloodspots to replace our current second-tier immunoassay method. The method was assessed using reference material and residual samples with a positive newborn screening result. Correlation with the second-tier immunoassay was determined and the method was implemented. Newborn screening performance was assessed by comparing screening metrics 2 years before and 2 years after LCMSMS implementation. Screening data analysis demonstrated the number of false positive screening tests was reduced from 172 to 40 in the 2 years after LCMSMS implementation. The positive predictive value of screening significantly increased from 1.71% to 11.1% (X2 test, p < 0.0001). LCMSMS analysis of 17OHP as a second-tier test significantly improves screening specificity for CAH due to 21-hydroxylase deficiency in New Zealand.

Topics & Concepts

Congenital adrenal hyperplasia21-HydroxylaseImmunoassayNewborn screeningHydroxyprogesteroneScreening testMedicinePredictive valueEndocrinologyInternal medicineObstetricsPediatricsAntibodyImmunologyHormoneSteroidSexual Differentiation and DisordersMetabolism and Genetic DisordersHormonal and reproductive studies