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Human-induced pluripotent stem cell lines (CMCi006-A and CMCi007-A) from a female and male patient with Fabry disease carrying the same frameshift deletion mutation

Sheng Cui, Yoo Jin Shin, Eun Jeong Ko, Sun Woo Lim, Ji Hyeon Ju, Kang In Lee, Jae Young Lee, Chul Woo Yang, Byung Ha Chung

2021Stem Cell Research11 citationsDOIOpen Access PDF

Abstract

Human-induced pluripotent stem cell lines (hiPSCs) derived from the peripheral blood mononuclear cells (PBMCs) of a woman (CMCi007-A) and her son (CMCi006-A) diagnosed with Fabry disease (FD) caused by the frameshift deletion mutation c.969delC in the alpha-galactosidase A (GLA) gene were generated. These hiPSCs showed typical human embryonic stem cell-like morphology and expressed pluripotency-associated markers, and directly differentiated into all three germ-layers. Karyotyping showed normal 46, XY (CMCi006-A) and 46, XX (CMCi007-A). In summary, we generated novel patient-specific hiPSC lines from both a female and male containing the same mutation, which may provide additional insight into the pathophysiology of FD.

Topics & Concepts

Frameshift mutationBiologyInduced pluripotent stem cellGerm layerMutationPeripheral blood mononuclear cellKaryotypeEmbryonic stem cellStem cellFabry diseaseMolecular biologyGeneticsGeneDiseaseChromosomePathologyIn vitroMedicineLysosomal Storage Disorders ResearchNeurogenetic and Muscular Disorders ResearchTrypanosoma species research and implications