Litcius/Paper detail

Successful treatment with anakinra in generalized spiculated porokeratosis and severe hidradenitis suppurativa in a patient with <i>MVK</i> and <i>MEFV</i> mutations

Ayşe Öktem, Günel Rasulova, Büşra Çavdarlı, Seher Bostancı, Aylın Okçu Heper, Seçil Vural

2022Clinical and Experimental Dermatology10 citationsDOI

Abstract

The synergistic effect of two mutations of the innate immune system may facilitate hyperactivation and dysregulation of the inflammasome in skin macrophages. This case connects two diseases, hidradenitis suppurativa and porokeratosis, by the central role of autoinflammation.

Topics & Concepts

Hidradenitis suppurativaMedicineDermatologyMEFVPityriasis rubra pilarisInflammasomePalmoplantar pustulosisAnakinraImmunologyMutationInflammationPsoriasisPathologyGene mutationDiseaseGeneticsBiologyGeneHidradenitis Suppurativa and TreatmentsAutoimmune and Inflammatory DisordersDermatological and Skeletal Disorders