Litcius/Paper detail

Diaphragm neuromuscular transmission failure in a mouse model of an early-onset neuromotor disorder

Matthew J. Fogarty, Joline E. Brandenburg, Gary C. Sieck

2020Journal of Applied Physiology17 citationsDOIOpen Access PDF

Abstract

Individuals with motor control deficits, including cerebral palsy (CP) often have respiratory impairments. Glycine-receptor mutant spa mice have early-onset hypertonia, and limb motor impairments, similar to individuals with CP. We hypothesized that in the diaphragm of spa mice, disruption of glycinergic inputs to MNs would result in increased phrenic–DIAm neuromuscular transmission failure. Pathophysiologic abnormalities in neuromuscular transmission may contribute to respiratory dysfunction in conditions where early developmental MN loss or motor control deficits are apparent.

Topics & Concepts

HypertoniaNeuromuscular transmissionCerebral palsyDiaphragm (acoustics)Glycine receptorRespiratory failurePathophysiologyNeuroscienceRespiratory systemMotor controlMedicineBulbar palsyPhysical medicine and rehabilitationPsychologyBiologyAnesthesiaInternal medicineGlycinePhysicsLoudspeakerAmino acidBiochemistryAcousticsNeurogenetic and Muscular Disorders ResearchCerebral Palsy and Movement DisordersNeuroscience of respiration and sleep